Case Report
Copyright ©The Author(s) 2018. Published by Baishideng Publishing Group Inc. All rights reserved.
World J Clin Cases. Nov 26, 2018; 6(14): 830-835
Published online Nov 26, 2018. doi: 10.12998/wjcc.v6.i14.830
Giant monostotic osteofibrous dysplasia of the ilium: A case report and review of literature
Yu-Bo Liu, Tian-Ming Zou
Yu-Bo Liu, Tian-Ming Zou, Department of Orthopedics, the Affiliated Suzhou Hospital of Nanjing Medical University, Suzhou 215002, Jiangsu Province, China
Author contributions: Both authors contributed to this manuscript.
Informed consent statement: Informed consent was obtained from the patient for publication of this report and any accompanying images.
CARE Checklist (2016) statement: The authors have read the CARE Checklist (2016), and the manuscript was prepared and revised according to the CARE Checklist.
Open-Access: This article is an open-access article which was selected by an in-house editor and fully peer-reviewed by external reviewers. It is distributed in accordance with the Creative Commons Attribution Non Commercial (CC BY-NC 4.0) license, which permits others to distribute, remix, adapt, build upon this work non-commercially, and license their derivative works on different terms, provided the original work is properly cited and the use is non-commercial. See: http://creativecommons.org/licenses/by-nc/4.0/
Correspondence to: Tian-Ming Zou, MD, Chief Doctor, Department of Orthopedics, the Affiliated Suzhou Hospital of Nanjing Medical University, No. 26 Daoqian Street, Suzhou 215002, Jiangsu Province, China. zoutianming@njmu.edu.cn
Telephone: +86-512-62362055 Fax: +86-512-62362502
Received: August 3, 2018
Peer-review started: August 4, 2018
First decision: September 11, 2018
Revised: September 15, 2018
Accepted: October 31, 2018
Article in press: November 1, 2018
Published online: November 26, 2018
Abstract
BACKGROUND

Osteofibrous dysplasia (OFD) is a developmental skeletal disorder, and cases with a giant affected area in the pelvis are rare.

CASE SUMMARY

In this case report, a 48-year-old man presented with a large tumor in the right iliac region that turned out to be OFD. The patient had rebound tenderness in his right hip. After radiography examination, magnetic resonance imaging examinations and some physical examination, extensive bone destruction in the right ilium was confirmed. Moreover, changes in bone mineral density and peripheral cortical bone sclerosis with surrounding soft tissue swelling were observed. Thus, this patient was considered to have giant monostotic OFD of the ilium. The tumor-related area was removed completely by surgery, and the remaining cavity was filled by artificial bones from the opposite ilium. According to the results of follow-up, the patient had normal flexion and extension activities of the right hip joint, and there was no evidence of recurrence of the tumor.

CONCLUSION

Suture of iliopsoas and gluteus medius muscle following focus curettage and bone grafting is a promising and effective method to treat giant OFD of the ilium. It is a feasible way to fill a large cavity after removing a lesion like the one is this case.

Keywords: Osteofibrous dysplasia, Monostotic type, Giant tumor, Ilium, Case report

Core tip: Osteofibrous dysplasia is a developmental skeletal disorder, and cases involving the pelvis with a large affected area are rare. This report is the first case, to our knowledge, of a 48-year-old man with a huge tumor in the right iliac that turned out to be osteofibrous dysplasia. With the assistance of computed tomography and magnetic resonance imaging, the tumor was completely removed, and the left empty cavity was reasonably filled by pulling and suturing nearby muscles and using some artificial bone.